Inotersen Preserves or Improves Quality of Life in Hereditary Transthyretin Amyloidosis

Key Information
Source
Journal of Neurology
Year
2020
summary/abstract

Hereditary transthyretin (hATTR) amyloidosis is a rare, systemic, progressive, debilitating, and fatal disease characterized by mutations in the gene encoding the transthyretin (TTR) protein. More than 130 reported TTR gene mutations promote misfolding of TTR proteins, which aggregate and deposit as insoluble amyloid deposits in tissues, inducing organ damage. Worldwide prevalence estimates indicate that approximately 50,000 people have been diagnosed with hATTR amyloidosis, although it is thought to be significantly underdiagnosed. Patients with hATTR amyloidosis typically suffer peripheral and autonomic nerve fiber injury, resulting in a length-dependent sensorimotor peripheral neuropathy, manifesting as pain, numbness, and weakness with eventual loss of ambulation. Others experience cardiomyopathy, characterized by conduction disease, thickening and stiffening of the ventricles, and eventual heart failure. The majority of patients, however, exhibit a mixed phenotype including nerve- and heart-related manifestations.

Abstract Source
https://www.ncbi.nlm.nih.gov/pmc/articles/PMC7109169/
DOI
10.1007/s00415-019-09671-9
Authors
Teresa Coelho, Aaron Yarlas, Marcia Waddington-Cruz, et al.
Organisation
Hospital Santo António, Portugal; Optum, USA; Hospital Universitário Clementino Fraga Filho, Brazil; Akcea Therapeutics, USA; Aurora Bio, USA; Otonomy, Inc., USA; Organovo Holdings, Inc., USA; Oregon Health and Science University, USA; University of Pennsylvania, USA; Mayo Clinic, USA; University of Pavia, Italy; University of Münster, Germany; Johns Hopkins University, USA; Mayo Clinic, USA; Columbia University, USA; Hospital de Santa Maria, Portugal; Indiana University, USA; Boston University, USA